Proton MR spectroscopy in Lesch-Nyhan disease.
نویسندگان
چکیده
In vivo proton spectra for four patients with Lesch-Nyhan disease and four control subjects matched for age and sex were acquired from voxels (1.5 x 1.5 x 1.5 cm3) placed in the prefrontal cortex and striatum. The patients with Lesch-Nyhan disease had decreased metabolites, especially N-acetylaspartate and glutamate/glutamine, only in the prefrontal cortex as compared with the control group. These findings suggest axonal loss in the prefrontal area of this population. The cortical glutamate/glutamine peak decrement does not confirm cytopathologic studies of Lesch-Nyhan disease and deserves further investigation.
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عنوان ژورنال:
- AJNR. American journal of neuroradiology
دوره 19 4 شماره
صفحات -
تاریخ انتشار 1998